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[P334] A case of adult myofibroma, clinically mimicking basal cell carcinoma
( Seong Hoon Seo ),( Jee Eun Kim ),( Soo- Chan Kim ) 대한피부과학회 2017 대한피부과학회 학술발표대회집 Vol.69 No.1
Myofibroma is fibroblastic-myofibroblastic tumor usually occurring in childhood. Adult myofibroma is considered as a counterpart of infantile myofibroma. Clinically, myofibroma typically presents as a solitary, firm and purplish nodule, sometimes with ulceration. Histologically, myofibroma is characterized by biphasic appearance with fascicles of spindle cells or hemangiopericytic appearance with less differentiated cells. Immunohistochemically, myofibroma is positive for vimentin, smooth muscle actin and negative for desmin. Herein, we report a case of adult myofibroma clinically resembling a basal cell carcinoma. A 37-year-old Korean male patient visited our clinic with a single erythematous pea-sized nodule with central depression on the right nasolabial fold. Biopsy was performed under impression of basal cell carcinoma. Tumor nodules with spindle cells were observed in the dermis. Immunohistochemistry study with smooth muscle actin was positive. Based on histopathologic and immunohistochemical analysis, the case was diagnosed as myofibroma. This case is an unusual adult myofibroma clinically mimicking basal cell carcinoma which was able to be diagnosed with histopathologic features and immunohistochemistry study.
[P053] A case of solitary adult type cutaneous myofibroma on the finger
( Si Hyub Lee ),( Ji Hye Heo ),( Hee Seong Yoon ),( Seung Dohn Yeom ),( Ji Won Byun ),( Gwang Seong Choi ),( Jeonghyun Shin ) 대한피부과학회 2017 대한피부과학회 학술발표대회집 Vol.69 No.1
Myofibroma is an uncommon, benign myofibroblastic neoplasm, mostly occurring on the skin. It can also involve skeletal muscles, bones, or viscera. Although adult-onset myofibroma shows histopathological similariry to infantile myofibromatosis, it has a distinct clinical feature compared with the infantile form. It is exclusively solitary, and usually affect the skin of head and neck, confined to the dermis and subcutaneous layer. Histopathologically, uncapsulated tumor in dermis consists of spindle shaped cells arranged in whorls or interlacing fascicles. The cytoplasms of the spindle shaped cells have fuchsinophilic appearance in Masson`s trichrome staining. Tumor cells show immune-reactivity to smooth muscle actin and vimentin, but negative to desmin and S-100. It does not regress spontaneously, but has benign clinical course with very rare recurrence after surgical treatment. Herein, we report a case of a solitary skin-colored hard keratotic papule that developed on the distal phalangeal joint area of left finger in a 58-year-old man. The tumor was diagnosed as cutaneous myofibroma by histopathologic examination and immunohistochemical stainings. This is the first case report about solitary cutaneous myofibroma of the finger in Korean dermatologic literature. The clinical manifestation of the lesion could be easily misdiagnosed as wart.
최성우,박종갑,김태윤,김형옥,김정원,강석진 ( Sung Woo Choi,Jong Gap Park,Tae Yoon Kim,Hyung Ok Kim,Chung Won Kim,Seok Jin Kang ) 대한피부과학회 1997 대한피부과학회지 Vol.35 No.5
Myofibroma and myofibromaiosis are uncommon, benign, mostly self-limiting, probably hamartomatous proliferation of myofibroblasts. These tumors are most often present at birth or before the age of 2 years with multiple ot solitary lesion. Adult cases are rare and most,ly showed as a solitary lesion. We present a case of solitary myofibroma that developed on the vertex of scalp in a 51-year-old man. The lesion was a mild tender and intermittent pruritic firm, pedunclated 1 1cm sized tumor. The iumor was diagnosed as myofibroma by light microscopy and immunohistochemistry. (Korean J Dermatol 1907;35(5): 1031-1035)
Myofibroma of the mandible : A case report
Kim, Jin-Soo,Kim, Sung-Eun,Kim, Jae-Duk 대한구강악안면방사선학회 2006 Imaging Science in Dentistry Vol.36 No.4
Myofibroma is a rare benign soft tissue tumor that in all ages usually occurs in the head and neck region, and at subcutaneous tissue, but rarely has bone origin within bone. Intraosseous lesions are more often found in childhood. Although intraosseous lesions are relatively common in mandible. Reports for mandible, reports on radiographic findings of myofibroma occurred on the mandible are uncommon. We describe the radiographic appearance on the conventional radiographs and CT of myofibroma of the mandible in a 9-year-old boy. This benign lesion closely resembles to odontogenic cyst or tumor on image.
Adult Solitary Myofibroma of the Mandible Mimicking a Periapical Lesion
윤정훈 대한구강악안면병리학회 2018 대한구강악안면병리학회지 Vol.42 No.5
Myofibroma is a benign tumor composed of fibroblasts and myofibroblasts, occasionally occurring most commonly as a solitary lesion of soft tissue, skin, or bone in children younger than 3 years of age. Solitary lesion of myofibroma is exceedingly rare in adult jaws. This report describes a rare case of myofibroma in the mandible that occurred in a 41-year-old Korean woman.
김성준,박현수,서승리,이용석,전덕규 대한피부과학회 2003 대한피부과학회지 Vol.41 No.2
Solitary myofibroma is an uncommon myofibroblastic neoplasm, presenting as an asymptomatic nodule of the skin, which mainly occurrs in adults. It was thought to be the adult counterpart of infantile myofibromatosis. Although it has histopathological similarity to infantile myofibromatosis, it shows a discrete clinicopathological entity compared with infantile form on the basis of its much later onset, superficial location, invariable solitary occurrence and uniformly benign behavior. A 45-year-old woman had a skin lesion on the right upper eyelid for 2 years, which was a solitary, painless nodule with eyelid retraction. The excised tumor was diagnosed as myofibroma by light microscopy and immunohistochemistry. (Korean J Dermatol 2003;41(2) : 272∼275)
윤정훈 대한구강악안면병리학회 2018 대한구강악안면병리학회지 Vol.42 No.5
Myofibroma is a benign tumor composed of fibroblasts and myofibroblasts, occasionally occurring most commonly as a solitary lesion of soft tissue, skin, or bone in children younger than 3 years of age. Solitary lesion of myofibroma is exceedingly rare in adult jaws. This report describes a rare case of myofibroma in the mandible that occurred in a 41-year-old Korean woman.
이정주,오병민,이석종,김도원,정상립,금윤섭 대한피부과학회 2002 大韓皮膚科學會誌 Vol.40 No.8
Solitary myofibroma is a recently described, benign neoplasm of superfical soft tissue, which represents the adult counterpart of infantile myofibromatosis. In Korean literature, only one case has been reported, and we report an additional case of solitary myofibroma in a 57-year-old man. He presented with 2-month history of asymptomatic slightly elevated pale-skin-colored nodule occurring on the right side of philtrum. A histopathologic examination revealed diffuse proliferation of fibroblasts and spindle cells with a whorled arrangement and grouped fascicles. The tumor cells were positively stained for vimentin and smooth muscle actin.
Two cases of infantile myofibroma mimicking congenital vascular tumors
( Min Ji Kim ),( Kyou Chae Lee ),( Sang Lim Kim ),( Yong Hyun Jang ),( Weon Ju Lee ),( Do Won Kim ),( Ho Yun Chung ),( Seok Jong Lee ) 대한피부과학회 2015 대한피부과학회 학술발표대회집 Vol.67 No.1
Infantile myofibroma(IM) is a rare benign tumor, which have been reported only 4 cases in Korean dermatologic literature since 1994. It can present solitary or multiple nodules over the entire body with or without visceral involvement such as a bone, lung, heart, and GIT, so can cause symptoms like a severe respiratory distress, vomiting or diarrhea. Prognosis is generally excellent if only a solitary nodule or multiple nodules limited to the skin are seen due to a high rate of spontaneous regression. Differential diagnosis of IM includes vascular tumor such as congenital hemangioma(CH) and infantile hemangiopericytoma. The patient 1 was a 2-week-old female, presented a solitary child fist sized dull-red rubbery nodule with central black eschar and purulent discharge on the right thigh since birth. After doppler USG, we performed diagnostic and therapeutic excision under impression of congenital epidermal cyst, rhabdomyosarcoma or CH. The patient 2 was a 1-month-old male, presented with several non-tender bean to walnut-sized dusky red firm nodules and subcutaneous masses on the neck root, extremities and flank. A skin biopsy was performed to identify the lesion. In second patient, whole body contrast CT proved that there is no involvement of visceral organ. Biopsy from the both patients were consistent with IM. Interestingly, second patient shows a slow overall spontaneous regression without any treatment based on regular follow up.