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최민주 ( Min Ju Choi ),서지명 ( Ji Myung Seo ),오상호 ( Sang Ho Oh ),김도영 ( Do Young Kim ) 대한피부과학회 2014 대한피부과학회지 Vol.52 No.9
Lupus miliaris disseminatus faciei (LMDF) is a chronic inflammatory disorder primarily affecting the face. A 22- year-old man presented with facial skin lesions. Physical examination revealed scattered pin-head sized erythematous to yellowish papules. Skin biopsy from the erythematous papule showed keratinous material in the layers of the thin epithelium and caseous necrosis with adjacent epitheloid granuloma and giant cells. After mechanical extractions of milium-like inflamed papules, skin lesions improved leaving an atrophic scar. LMDF was initially thought to be associated with tuberculosis infection but today it is considered a variant of rosacea. However, there have been reports of LMDF in association with epidermal cysts or milium, suggesting an abnormal immune response to the pilosebaceous unit may play a role. Damage to the pilosebaceous unit that is further complicated by milium rupture may induce inflammation resulting in LMDF. We suggest that milium or epidermal cysts may also attribute to the pathogenesis of LMDF although further studies are needed. (Korean J Dermatol 2014;52(9):638∼641)
[P436] A case of milium-like syringoma
( Jin Yong Lee ),( Young Her ),( Kang Su Kim ),( Ji Eun Hahm ),( Jae Won Ha ),( Chul Woo Kim ),( Sang Seok Kim ) 대한피부과학회 2017 대한피부과학회 학술발표대회집 Vol.69 No.1
Syringoma is a benign tumor derived from the intraepidermal eccrine ducts, and milium is a tiny epidermoid cyst containing keratinous materials. Milium-like syringoma (MLS) is a rare variant of syringoma combining these two distinctive entities. They are commonly localized to one focal body area such as the periorbits, axilla, trunk, and genital area. However, MLS limited only to the neck is extremely rare. Here, we present the case who developed MLS limited to the anterior neck. A healthy 30-year-old Korean woman presented with 1-2 mm yellowish shiny flat-topped papules in groups on her anterior neck. The patient reported that the lesions had slightly increased in number over the last 8 years with no symptoms. On examination, the papules showed a well-demarcated pearl-like appearance suggesting milia or flat warts. The histopathology revealed a syringoma with a cyst containing laminated keratinous materials. Numerous small ducts with comma-like tails of epidermal strands were found in the fibrotic stroma. Immunohistochemically, both the keratinous cyst and underlying epithelial cells were negative for CK7 and Fontana-Masson but were positive for carcinoembryonic antigen(CEA). Therefore, we diagnosed the lesion as an MLS.
김영훈 ( Young Hun Kim ),이영규 ( Yeong Kyu Lee ),최규원 ( Kyu Won Choi ),이채욱 ( Chae Wook Lee ),김기호 ( Ki Ho Kim ) 대한피부과학회 2008 대한피부과학회지 Vol.46 No.2
Milium-like syringoma is a rare variant of syringoma first described by Friedman and Butler in 1987. Clinically, it presents as milium, but histologically reveals syringoma with overlying keratin filled epidermoid cysts. It occurs predominantly on the periorbital area of middle-aged women. Syringomas on the genital area have rarely been reported. The lower portion of the cysts and keratin materials show positivity for CEA and negativity for CK7. The pathogenesis is not well defined, but there are some hypotheses, which include pruritus and increasing hormonal receptors (estrogen and progesterone receptors). We report a case of milium-like syringoma on the vulva. (Korean J Dermatol 2008;46(2):245∼248)
Case Report : A Case of Scrotal Calcinosis Originating from a Milium-like Syringoma
( Jae Hyung Lee ),( Ji Hye Park ),( Jae Ho Lee ),( You Jin Lee ),( Jong Yoon Chung ),( Hae Young Park ),( Jong Hee Lee ),( Joo Heung Lee ),( Jun Mo Yang ),( Dong Youn Lee ) 대한피부과학회 2015 大韓皮膚科學會誌 Vol.53 No.5
Scrotal calcinosis is a relatively common tumor of the male genitalia but there is controversy in the literature regarding its pathogenesis. The authors of many case reports debate whether the lesions are truly idiopathic or if they arise from other conditions. Only few cases of scrotal calcinosis have been proven to have an eccrine origin so far. Herein, we report a case of scrotal calcinosis originating from a milium-like syringoma in a male Korean patient. (Korean J Dermatol 2015;53(5):400∼402)
전수일(Soo Il Chun),강원형(Won Hyoung Kang),황규광(Kyu Kwang Whang) 대한피부과학회 1986 대한피부과학회지 Vol.24 No.2
Ultrastructural study was taken in a 48 year old male farmer with colloid milium. Electrcn microscopically, colloid was mainly composed of protofilaments, amorphous substance and degenerating collagens surrounded by halos. Colloidal filaments were curved and branched at their ends. Fibroblasts near the colloid island contained amorphous materials and protofilaments idnitical to that of colloid materials, Thus we suggest that. colloid milium may be produced by the abnormal fibroblasts or may be derived from actiinically damaged collagen fibers.
이정연 ( Jung Yeon Lee ),이시현 ( See Hyun Lee ),최연진 ( Yeon Jin Choi ),신미선 ( Mi Seon Shin ),안지영 ( Ji Young Ahn ),박미연 ( Mi Youn Park ) 大韓皮膚科學會 2009 大韓皮膚科學會誌 Vol.47 No.12
We report here on a 71-year-old female who had well-demarcated erythematous patches, along with some pearly papules, on the right cheek. Histopathological examination of the lesions revealed a basaloid cell mass, which appeared to be a superficial basal cell carcinoma, and a small keratin-filled cyst that appeared to be a milium. A part of the milium was surrounded by the basaloid cells of tumor islands and milia later developed on the lesion of basal cell carcinoma. We suggest that basal cell carcinoma may be one of the causes of secondary milia. (Korean J Dermatol 2009;47(12):1397∼1399)
Tranilast로 치료한 소아 외음부 비립종양 한관종 1예
권원주 ( Won Joo Kwon ),신요섭 ( Yo Sup Shin ),박복원 ( Bok Won Park ),조은별 ( Eun Byul Cho ),박은주 ( Eun Joo Park ),김광호 ( Kwang Ho Kim ),김광중 ( Kwang Joong Kim ) 대한피부과학회 2017 대한피부과학회지 Vol.55 No.8
Syringoma is the most common type of benign intraepidermal eccrine sweat gland tumor in Korea, and is usually found in women in their forties. It presents mostly as a localized lesion, preferring the lower eyelid, cheek, or forehead, and rarely invades the vulval area, and in the case of children, vulvar invasion is even more rare. Tranilast is an antihistamine used for atopic dermatitis and asthma, and has recently been used for the treatment of keloid. A few previous studies have reported both localized and generalized forms of syringoma being effectively resolved with tranilast. Herein, we report a rare and interesting case of milium-like syringoma, which manifested on the vulval area of 10-year old girl that was successfully treated with tranilast. (Korean J Dermatol 2017;55(8):526∼ 528)
A case of chronic relapsing pseudolymphoma caused by ruptured milia
( Minseok Lee ),( Young In Lee ),( Do Young Kim ) 대한피부과학회 2015 대한피부과학회 학술발표대회집 Vol.67 No.1
Cutaneous pseudolymphomas are inflammatory conditions that result from benign reactive proliferation of lymphocytes. Most cases of pseudolymphoma are idiopathic, however many known inciting agents have been reported. Herein, we report an interesting case of recurrent pseudolymphoma caused by the rupture of multiple milia. A 72-year old female visited our clinic for a 6 year history of multiple erythematous confluent plaques on the forehead and left face. Histopathology revealed nodular lymphoid hyperplasia suggesting pseudolymphoma. The lesions were persisted with recurrence. On close observation, newly developed pseudolymphoma-like lesion was contiguous to a milium. Biopsy from new lesion showed a dense lymphohisticocytic infiltration around a ruptured milium. Pseudolymphoma has been described to be associated with medications, arthropod assaults, infection, foreign body, tattoo and traumas. There are several case reports that pseudolymphomas can arise from common skin disease such as folliculitis. However, to our knowledge, there have been no reports with multiple milia resulting in recurrent pseudolymphoma. Our case suggests that milia, a common dermatosis, can be a plausible cause of chronic pseudolymphoma.