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A typical case of BCGitis in a French child
( Hyunji Lee ),( Ju Hee Han ),( Hyun Min Seo ),( Ji Hyun Lee ),( Jun Young Lee ),( Young Min Park ) 대한피부과학회 2016 대한피부과학회 학술발표대회집 Vol.68 No.1
Abnormal cutaneous reaction after Bacillus Calmette-Guerin (BCG) vaccination includes erythema, ulceration, blistering, keloid formation, epithelial cysts and granuloma formation at injection site. Specific cutaneous reactions are caused by infection of attenuated Mycobacterium bovis from the vaccine, and mimic true cutaneous tuberculosis. This is called BCG-itis in existing literature. Risk factors for the development of BCGitis are immunodeficiency, age less than 1 month at time of injection and subcutaneous application of the vaccine. Herein, we report on a rare case of BCGitis. A 25-month-old French child presented with a 1.8 cm-sized, erythematous plaque with central ulceration of the Lt. upper arm for two months. He had received injection of BCG inoculation five months ago. Histopathologic examination showed the characteristic features of cutaneous tuberculosis with caseous necrosis in deep dermis. The result of polymerase chain reaction (PCR) detected be Mycobacterium tuberculosis. These findings were well consistent with BCGitis. The lesion was almost improved after treatment with isoniazide 120 mg daily for two months.
Omphalolith associated with urachal remnant
( Hyunji Lee ),( Ju Hee Han ),( Hyun Min Seo ),( Ji Hyun Lee ),( Jun Young Lee ),( Young Min Park ) 대한피부과학회 2016 대한피부과학회 학술발표대회집 Vol.68 No.1
An omphalolith is an accumulation of sebum and keratin leading to the formation of a calculus. Lack of umbilical hygiene and deep umbilical cleft can be predisposed to this condition. To our knowledge, only one case of omphalolith associated with urachal sinus has been reported in English literature. Herein we report on a rare case of omphalolith associated with urachal remnant in a young Korean woman. A 25-year-old Korean woman presented with a solitary, asymptomatic, 1 cm-sized, pigmented mass of 5-year duration in the umbilicus. The mass was firm to hard on palpation, and had a dry crusted appearance. She had a history of continuous discharge through the umbilicus and the mass recurred despite self-removal. The histopathological examination of the specimen revealed concentric lamellae of keratin, which were consistent with omphalolith. The abdominal computerized tomography scan demonstrated a thickened tubular structure along the midline below the umbilicus, suggesting an urachal remnant. Because the patent embryonic urachal remnant was thought to be the cause of the omphalolith formation in this case, we recommended surgical excision, but she refused the operation.
Foreign body granuloma induced by squalene injection
( Hyunji Lee ),( Ju Hee Han ),( Hyun Min Seo ),( Ji Hyun Lee ),( Jun Young Lee ),( Young Min Park ) 대한피부과학회 2016 대한피부과학회 학술발표대회집 Vol.68 No.1
Squalene, an isoprenoid compound structurally similar to beta-carotene, is an intermediate metabolite in the synthesis of cholesterol. In humans, the greatest concentration of squalene is in the skin, where it is one of the major components of skin surface lipids. Recently, it is indiscriminately used as not only health food but also as cosmetic purpose without scientific basis. Herein we report on an interesting case of foreign body granuloma as one of the potential complications of squalene injection. A 28-year-old Korean woman presented with multiple, pruritic, 1 cm-sized, round-shape, erythematous nodules which had developed on the forehead for 1 week. She had a history of laser epilation on the forehead 1 month ago and then she also had received squalene injection on the same area 2 weeks ago. The histopathological examination of the representative lesion showed a moderate-to-marked lymphohistiocytic infiltration and a focal granuloma formation with multinucleated giant cells in the dermis. Ziehl-Neelsen stain and polymerase chain reaction for M. tuberculosis showed negative results. These findings were consistent with foreign body granuloma after squalene injection. After treatment with 3 days of prednisolone 10 mg/day, she was lost to follow-up.
Periorbital lipogranuloma caused by autologous fat injection for facial augmentation
( Hyunji Lee ),( Ju Hee Han ),( Hyun Min Seo ),( Ji Hyun Lee ),( Jun Young Lee ),( Young Min Park ) 대한피부과학회 2016 대한피부과학회 학술발표대회집 Vol.68 No.1
Autologous fat injection has been increasingly popular in recent years. Generally, autologous fat injection provides good results, but few complications such as hematoma, skin contour irregularities, or fat embolism have been reported. This case illustrates the importance of considering lipogranuloma in patients presenting with newly developed facial mass. To the best of our knowledge, this is the first reported case of lipogranuloma caused by autologous fat injection in the Korean dermatologic literature. A 50-year-old woman presented with two, 0.1~0.2cm sized, skin-colored subcutaneous masses at infero-medial side of left periorbital area detected 1 month ago. This patient had received autologous fat injection on the periorbital areas, cheeks and forehead at a local plastic surgery clinic 12months ago. A skin biopsy specimen showed numerous, variable-sized lipid vacuoles surrounded by histiocytes and lymphocytes with the areas of fibrosis and fat necrosis. The lesions were completely removed by biopsy and there was no recurrence after 6-month follow-up.
Distinct Features of Nonthyroidal Illness in Critically Ill Patients With Infectious Diseases
Lee, Woo Kyung,Hwang, Sena,Kim, Daham,Lee, Seul Gi,Jeong, Seonhyang,Seol, Mi-Youn,Kim, Hyunji,Ku, Cheol Ryong,Shin, Dong Yeop,Chung, Woong Youn,Lee, Eun Jig,Lee, Jandee,Jo, Young Suk Wolters Kluwer Health 2016 Medicine Vol.95 No.14
<▼1><P>Supplemental Digital Content is available in the text</P></▼1><▼2><P><B>Abstract</B></P><P>Nonthyroidal illness (NTI), often observed in critically ill patients, arises through diverse alterations in the hypothalamus-pituitary-thyroid (HPT) axis. However, the causal relationship between underlying disease and NTI diversity in critically ill patients is poorly understood.</P><P>The aim of this study was to examine NTI severity and adverse outcomes in critically ill patients with respect to their underlying disease(s).</P><P>The medical records of 616 patients admitted to the intensive care unit (ICU) between January 2009 and October 2014 were retrospectively reviewed. Patients with known diseases or taking medications that affect thyroid function were excluded. All-cause mortality (ACM) and length of stay (LOS) in the ICU were assessed as adverse outcomes.</P><P>The enrolled patients (n = 213) were divided into the following 4 groups according to the severity of NTI at the nadir of their thyroid function test (TFT): normal (n = 11, 5.2%), mild NTI (n = 113, 53.1%), moderate NTI (n = 78, 36.6%), and severe NTI (n = 11, 5.2%). There was no significant difference between the groups in terms of age and gender. NTI severity showed a significantly strong association with ACM (<I>P</I> < 0.0001) and a significant positive association with LOS in the ICU (<I>P</I> = 0.031). After adjusting for age, gender, and current medications affecting TFT, increasing NTI severity led to increased ACM (odds ratio = 3.101; 95% confidence interval = 1.711–5.618; <I>P</I> < 0.0001). Notably, the prevalence of moderate-to-severe NTI was markedly higher in patients with infectious disease than in those with noninfectious disease (<I>P</I> = 0.012). Consistent with this, serum C-reactive protein levels were higher in patients with moderate-to-severe NTI (<I>P</I> = 0.016).</P><P>NTI severity is associated with increased ACM, LOS, and underlying infectious disease. Future studies will focus on the biological and clinical implications of infectious disease on the HPT axis.</P></▼2>
Nail unit Bowen`s disease presented as longitudinal melanonychia
( Hyunji Lee ),( Ju Hee Han ),( Hyun Min Seo ),( Ji Hyun Lee ),( Jun Young Lee ),( Young Min Park ) 대한피부과학회 2016 대한피부과학회 학술발표대회집 Vol.68 No.1
Bowen’s disease (BD) is uncommon in the nail unit and periungual areas. BD of the nail unit has multiple clinical presentations, which often makes diagnosis challenging. It can present as hyperkeratotic, papillomatous, or warty proliferations, erosions or scaling of the nail fold, or ulceration of the lateral nail groove, sometimes with granulation-like tissue underneath. Rarely, longitudinal melanonychia has also been reported as a presentation of BD of the nail unit. Herein we report on a rare case of nail unit BD presented as longitudinal melanonychia. A 62-year-old man presented with 3-months history of longitudinal melanonychia with mild hyperkeratotic change on the lateral aspect of his right second fingernail. We performed a biopsy on the nail plate with nail bed after partially extracting the finger nail. Histopathological findings revealed a marked acanthotic epidermis with full-thickness disorganization with atypical keratinocytes. There was no increase of melanin pigment and melanocytes in the epidermis. We recommend the patient a surgical excision such as Mohs surgery due to the possibility of a development of the invasive carcinoma.