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하태영,이상수,이무형,허충림 ( Tai Young Har,Sang Soo Lee,Moo Hyung Lee,Choong Rim Haw ) 대한피부과학회 1988 대한피부과학회지 Vol.26 No.2
We report a case of Darier's disease occuring in 49-year-old female patient. She had hyperkeratotic crusted eruptions on her forehead, neck and posterior auricular area. The skin lesions aggravated in summer and improved in winter, but never been healed completely. Histopathologic features from neck lesions revealed hyperkeratosis with corps ronds and grains as well as formation of villi and laeunae. We treated her with oral etretinate, and she was almost completely free of disease after 3 months treatment. We suggested that etretinate is an importnat advance in the treatment of Darier's disease.
오희수(Hee Soo Oh),이무형(Moo Hyung Lee),김낙인(Nack In Kim),허충림(Choong Rim Haw) 대한피부과학회 1988 대한피부과학회지 Vol.26 No.4
We report a case of pseudoxanthomatous mastocytosis that is an uncommon variant of urticaria pigmentosa. A 3 month-old boy visited our hospital with yellowish cutaneous nodules At the age of 2 months, small yellowish macule developed on the posterior neek, and during the following months, lesions spread to trunk, upper extremities, face, and scalp, most of them became gradually to the nodules. Darier's sign could be elicited easily. A biopsy of one. of the nodules or the back showed a very dense oval or cuboidal cells infiltrate in the dermis. Special stain with toluiddine blue showed this to he composed of mast cells. Electron microscopic examination revealed crowded mast. cells which was showing numerous cytoplasmic granules and long, thin villi. The patient: was managed symptomaticvlly and recommended to avoid mechanical or chemical irritation to the lesions.
하태영(Tae Young Har),이무형(Moo Hyung Lee),김낙인(Nack In Kim),허충림(Choong Rim Haw) 대한피부과학회 1987 대한피부과학회지 Vol.25 No.2
We report herein a caae of linear scleroderma resembling pseudoainhum. The patient was a 17-year-old boy who has 10 years history of linear, ivory colored, atraphic patch on his left 4th finger and left arm. The lesion was progreased slowly, and 2 years before he visited our hospital, his left 4th finger was amputated spontaneously. In histopathological examination, packed collagen, thick collagen bundle in dermis, and large areas of subcutaneous fat were replaced by eollagen fiber. Diagnosis was confirmed by the characteristics of clinical features and histopathologic findings of the skin. As therapeutic trials, steroid intralesional injection, immunotherapy with levamisole, agd penicillamine were attempted.
이상수(Sang Soo Lee),이무형(Moo Hyung Lee),김낙인(Nack In Kim) 대한피부과학회 1988 대한피부과학회지 Vol.26 No.4
Sebaceous epithelioma is an uncommon and primary neoplasm of sebaceous gland. We report herein a case of sebaceous epithelioma in an 85-year-old female. Physical examination showed a solitary, 2.5 x 3.5cm sized, reddish. irregularly surfaced, and well defined tumor on the intercanthal area. Histopathological findings showed tumor parenchyma. romprised of several large nests of three kinds of epithelial cells, mature sebaceous cells, undifferentiated cells arranged in pa1isade fashion at the periphery of a cell nest, and transitiornal cells showing beginning fatty vacuolizatiorn of the cytoplasm. Electron micocopy revealed immature dark cells, transitional cells, and mature sebaceous cell which showed many scattered foci of sebaceous ditferentiation characterized by intracytoplasmic lipid droplets and glycogen particls.
Etretinate 경구 투여로 호전을 보인 모공성 홍색 비강진
이봉구(Bong Goo Lee),이무형(Moo Hyung Lee),김낙인(Nack In Kim),허충림(Choong Rim Haw) 대한피부과학회 1987 대한피부과학회지 Vol.25 No.6
We report herein a case of pityriasis rubra pilaris in a 39-year-old male, who had erythematous scaly patches on the face, trunk and extremities for one year. The skin lesion showed well defined plaques on the elbow and knee joint areas, and exfoliative hyperkeratotic sheets with fissures on the palms and soles. He had no family and past history of such skin lesion. He was treated with etretinate lmg/kg/day for 1 week initially, and then tapered off 0.5mg/kg/day for 5 weeks with marked improvement. There was no exacerbation and recurrence of the skin lesion for about 1 year.